Paeds Vivas · genetics-dysmorphology-and-metabolism
Lysosomal storage disorders — branching viva
Branching viva on the lysosomal storage disorders: recognising the cardinal clinical patterns, classifying by stored substrate, confirming with a layered enzyme-and-genotype workup, and matching the disease-modifying therapy to central-nervous-system involvement.
On this page
Study tools
Target exams
Opening branch — the regressing infant with hepatosplenomegaly
A four-month-old who was meeting milestones now regresses over six weeks, with irritability, spastic limbs, and a liver edge 5 cm below the costal margin. The candidate must give a unifying diagnosis of a neuronopathic lysosomal storage disorder, name the sphingolipidosis substrate group, and justify the urgency: the rapid neurodegeneration narrows the window for a disease-modifying transplant, so the confirmatory workup must be completed within days. [1] [3]
The examiner probes the investigation strategy. The candidate gives the layered approach — urine glycosaminoglycans and oligosaccharides first, then leucocyte enzyme activity, then molecular gene-panel confirmation — and explains why a single low enzyme on a newborn bloodspot is a screen rather than a diagnosis, with pseudodeficiency alleles and late-onset variants producing abnormal screens in children who may never become unwell. [2] [5]
References5ShowHide
- [1]Platt FM, d'Azzo A, Davidson BL, Neufeld EF, Tifft CJ. Lysosomal storage diseases. Nat Rev Dis Primers, 2018.PMID 30275469
- [2]Parenti G, Andria G, Ballabio A. Lysosomal storage diseases: from pathophysiology to therapy. Annu Rev Med, 2015.PMID 25587658
- [3]Staretz-Chacham O, Lang TC, LaMarca ME, Krasnewich D, Sidransky E. Lysosomal storage disorders in the newborn. Pediatrics, 2009.PMID 19336380
- [4]Kishnani PS, Steiner RD, Bali D, et al. Pompe disease diagnosis and management guideline. Genet Med, 2006.PMID 16702877
- [5]Kwon JM, Matern D, Kurtzberg J, et al. Consensus guidelines for newborn screening, diagnosis and treatment of infantile Krabbe disease. Orphanet J Rare Dis, 2018.PMID 29391017